Letter

Red Blood Cell Distribution Width as a Biomarker of Red Cell Dysfunction Associated with Inflammation and Macrophage Iron Retention: A Prognostic Marker in Heart Failure and a Potential Predictor for Iron Replacement Responsiveness

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Correspondence Details:Artemio García-Escobar, Quirónsalud University Hospital Madrid, Calle Diego de Velázquez, 1, 28223 Pozuelo de Alarcón, Madrid, Spain. E: dr_garciaescobar@hotmail.com

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This work is open access under the CC-BY-NC 4.0 License which allows users to copy, redistribute and make derivative works for non-commercial purposes, provided the original work is cited correctly.

Dear Editor,

We read with great interest the review article by Alzaabi et al., which discusses multiple biomarkers associated with heart failure (HF), including those related to oxidative stress, the extracellular matrix, renal function, inflammation, cardiac peptides and other novel biomarkers.1 The authors describe the clinical implications of these biomarkers for evaluating the risk of HF development as well as HF severity, prognosis and therapy responsiveness.1 In this letter, we highlight elevated red cell distribution width (RDW) as a prognostic marker in HF and a potential predictor of therapy responsiveness.2 We review the most relevant studies regarding RDW as a prognostic marker in HF, discuss mechanisms responsible for RDW elevation and explore the relationship between high RDW and HF.

RDW measures the heterogeneity of the distribution of red blood cell size. The term ‘width’ is misleading, as the value is not derived from the width of the red blood cells (RBC), but rather from the width of the distribution curve of the corpuscular volume. A high RDW, therefore, implies a large variation in RBC size that is also known as anisocytosis, and a low RDW indicates a more homogeneous population of RBC sizes.2,3 RDW is routinely assessed as part of the complete blood count and is calculated as RDW = (SD/mean corpuscular volume) × 100, with reference values of approximately 11–15%.4

Hepcidin is a 25 amino acid peptide hormone produced by the liver. It is the main regulator of iron homeostasis under various pathological conditions and affects both erythropoiesis and RBC turnover rate.5 Hepcidin binds the iron exporter ferroportin, which is expressed in enterocytes, macrophages, hepatocytes and erythrocytes.6 Hepcidin mRNA expression decreases during hypoxaemia due to decreased ambient oxygen or to anaemia caused by bleeding or haemolysis. Conversely, hepcidin mRNA expression increases in response to inflammation and increasing serum iron levels.5,6 A different variation in the size of the RBC population generates a high RDW.2–4

Hypoxia can lead to the production of hypoxia-inducible factors, which increase erythropoietin (EPO) production depending on the severity of hypoxaemia. EPO production can enhance the self-renewal of colony-forming unit-erythroid by approximately 170-fold, causing the early release of young cells into circulation.7 A cohort study of patients admitted to intensive care with acute respiratory failure found that reticulocyte levels gradually increased as RDW rose.8 Therefore, EPO not only increases the rate of RBC formation but also the volume of RBCs, resulting in a higher RDW.9 Hence, either the downregulation or upregulation of hepcidin can produce a high RDW (Figure 1).

Figure 1: Hepcidin Regulation Pathways

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Considerable evidence supports the role of interleukin (IL)-6 in regulating hepcidin expression by directly binding of signal transducer and activator of transcription 3.10 IL-6 is a well-known cytokine that plays an important role in chronic inflammation states, such as infection, cancer, immune-related disorders, diabetes, HF and cardiovascular disease.11–14

From a practical perspective, a high RDW can be due to ineffective erythropoiesis, inflammation, hypoxaemia and/or impaired iron availability.2,3 Therefore, RDW is not specific to HF since an elevated RDW can be associated with haematologic and autoimmune disorders, oncological disease, critical conditions such as systemic inflammatory response syndrome and acute respiratory distress syndrome, acute bleeding or transfusions.2,3,9,15–18 Numerous studies have shown that an elevated RDW is associated with an increased risk of all-cause mortality and adverse cardiovascular events, such as MI, stroke and hospitalisation due to HF decompensation. Additionally, elevated RDW has been linked to an increased risk of AF, with some studies suggesting it is a potential predictor of AF recurrence after catheter ablation.2,3,19,20 An elevated RDW is, therefore, a prognostic marker in HF (Table 1). Moreover, a cohort study in Massachusetts reported that high RDW is associated with an increased mortality risk for patients with COVID-19; patients whose RDW increased during the first week of admission experienced higher mortality rates than those whose RDW remained stable. Increased mortality was related to hypoxaemia, impaired iron availability, elevated ferritin levels and increased IL-6 due to high systemic inflammation, a common occurrence in acute distress respiratory syndrome with or without COVID-19.21,22 The study demonstrated that RDW increases in both chronic and acute inflammatory states.21

Table 1: Studies Related to Red Cell Volume Distribution Width and its Association with Prognosis in Heart Failure

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Iron deficiency (ID) is found in 37–50% of patients with stable chronic HF, suggesting dysregulation of iron metabolism in HF.23,24 It is unclear whether these changes are maladaptive and pathologic, or compensatory and protective for the cardiomyocytes. Furthermore, macrophages play an important role in iron homeostasis by storing excess iron in iron overload diseases or promoting iron retention in chronic inflammatory conditions such as HF.10,14 This process is mediated by IL-6, which upregulates the hepcidin–iron axis.10,14,25 High RDW can occur in ID, which can be either absolute (low ferritin) or functional (normal/high ferritin), with or without concurrent anaemia.25,26 Contemporary HF research leans toward transferrin saturation (TSAT) as a better and more appropriate marker of functional ID than ferritin.27

Large-scale clinical trials have demonstrated improvements in New York Heart Association functional classification following iron replacement therapy in patients with HF and iron deficiency.28–30 Accordingly, the European Society of Cardiology guidelines recommend iron replacement therapy in patients with HF and ID, defined as serum ferritin <100 μg/l or ferritin ≥100 μg/l and TSAT <20%.31 Interestingly, a sub-analysis of the FAIR-HF study revealed that high RDW was associated with decreased TSAT and increased C-reactive protein. Treatment with intravenous ferric carboxymaltose in patients with ID and chronic HF reduced RDW. Furthermore, the increase in 6-minute walk test distance after 24 weeks was significantly correlated with a decrease in RDW (r=−0.25, p<0.0001), even after adjusting for changes in haemoglobin.32

From our perspective, the mechanisms of progressive HF may be intertwined with increasing myocardial iron deficiency, which is associated with reduced myocardial oxygen consumption and impaired myocardial metabolism, leading to a worse prognosis. It is, therefore, crucial to identify patients with ID and closely monitor their treatment response.

Notably, some studies have demonstrated that high RDW correlates with increasing IL-6 and impaired iron availability due to iron retention by macrophages.20,33,34 Consistent with this, the BioStat-CHF study reported that elevated IL-6 levels were found in over 50% of patients and were associated with ID.14 Consequently, RDW serves as a highly sensitive marker for ID.35

Progressive renal and hepatic dysfunction, decreased peak oxygen uptake, and high systemic inflammation are commonly seen in advanced HF and can contribute to ineffective erythropoiesis.36

In conclusion, RDW is a biomarker of red blood cell dysfunction, indicating elevated systemic inflammation, hypoxemia and/or ID. ID may be absolute or functional, the latter due to impaired iron mobilisation from stores caused by inflammation-driven factors, including IL-6, hepcidin and macrophage iron retention. Finally, RDW stands out as a valuable marker because it is included in routine full blood counts, making it both low-cost and easy to obtain at the bedside. From a clinical perspective, an elevated RDW implicates a worse HF prognosis due to an increased risk of both all-cause mortality and adverse cardiovascular events. Patients with a high RDW may also have ID and be at risk for developing ineffective erythropoiesis. Moreover, in patients with ID confirmed by serum ferritin <100 μg/l or TSAT <20%, a reduced RDW following iron replacement therapy is associated with clinical improvement. Thus, RDW may also predict iron replacement responsiveness in HF.

References

  1. Alzaabi MA, Abdelsalam A, Alhammadi M, et al. Evaluating biomarkers as tools for early detection and prognosis of heart failure: a comprehensive review. Card Fail Rev 2024;10:e06. 
    Crossref | PubMed
  2. García-Escobar A, Grande Ingelmo JM. Red cell volume distribution width as another biomarker. Card Fail Rev 2019;5:176–9. 
    Crossref | PubMed
  3. García-Escobar A, Lázaro-García R, Goicolea-Ruigómez J, et al. Red blood cell distribution width is a biomarker of red cell dysfunction associated with high systemic inflammation and a prognostic marker in heart failure and cardiovascular disease: a potential predictor of atrial fibrillation recurrence. High Blood Press Cardiovasc Prev 2024;31:437–49. 
    Crossref | PubMed
  4. Evans TC, Jehle D. The red blood cell distribution width. J Emerg Med 1991;9(Suppl 1):71–4. 
    Crossref | PubMed
  5. Nicolas G, Chauvet C, Viatte L, et al. The gene encoding the iron regulatory peptide hepcidin is regulated by anemia, hypoxia, and inflammation. J Clin Invest 2002;110:1037–44. 
    Crossref | PubMed
  6. Armitage AE, Eddowes LA, Gileadi U, et al. Hepcidin regulation by innate immune and infectious stimuli. Blood 2011;118:4129–39. 
    Crossref | PubMed
  7. Hattangadi SM, Wong P, Zhang L, et al. From stem cell to red cell: regulation of erythropoiesis at multiple levels by multiple proteins, RNAs, and chromatin modifications. Blood 2011;118:6258–68. 
    Crossref | PubMed
  8. Zhang W, Wang Y, Wang J, Wang S. Association between red blood cell distribution width and long-term mortality in acute respiratory failure patients. Sci Rep 2020;10:21185. 
    Crossref | PubMed
  9. Yčas JW, Horrow JC, Horne BD. Persistent increase in red cell size distribution width after acute diseases: a biomarker of hypoxemia? Clin Chim Acta 2015;448:107–17. 
    Crossref | PubMed
  10. Wrighting DM, Andrews NC. Interleukin-6 induces hepcidin expression through STAT3. Blood 2006;108:3204–9. 
    Crossref | PubMed
  11. Jones SA, Jenkins BJ. Recent insights into targeting the IL-6 cytokine family in inflammatory diseases and cancer. Nat Rev Immunol 2018;18:773–89. 
    Crossref | PubMed
  12. Rosa M, Chignon A, Li Z, et al. A Mendelian randomization study of IL6 signaling in cardiovascular diseases, immune-related disorders and longevity. NPJ Genom Med 2019;4:23. 
    Crossref | PubMed
  13. Chen YL, Qiao YC, Pan YH, et al. Correlation between serum interleukin-6 level and type 1 diabetes mellitus: a systematic review and meta-analysis. Cytokine 2017;94:14–20. 
    Crossref | PubMed
  14. Markousis-Mavrogenis G, Tromp J, Ouwerkerk W, et al. The clinical significance of interleukin-6 in heart failure: results from the BioStat-CHF study. Eur J Heart Fail 2019;21:965–73. 
    Crossref | PubMed
  15. Ai L, Mu S, Hu Y. Prognostic role of RDW in hematological malignancies: a systematic review and meta-analysis. Cancer Cell Int 2018;18:61. 
    Crossref | PubMed
  16. Alghamdi M. Red blood cell distribution width: a potential inexpensive marker for disease activity in patients with rheumatic diseases; scoping review. Open Access Rheumatol 2023;15:173–80. 
    Crossref | PubMed
  17. Pilling LC, Atkins JL, Kuchel GA, et al. Red cell distribution width and common disease onsets in 240,477 healthy volunteers followed for up to 9 years. PLOS ONE 2018;13:e0203504. 
    Crossref | PubMed
  18. Kim CH, Park JT, Kim EJ, et al. An increase in red blood cell distribution width from baseline predicts mortality in patients with severe sepsis or septic shock. Crit Care 2013;17:R282. 
    Crossref | PubMed
  19. Tonelli M, Sacks F, Arnold M, et al. Relation between red blood cell distribution width and cardiovascular event rate in people with coronary disease. Circulation 2008;117:163–8. 
    Crossref | PubMed
  20. Allen LA, Felker GM, Mehra MR, et al. Validation and potential mechanisms of red cell distribution width as a prognostic marker in heart failure. J Card Fail 2010;16:230–8. 
    Crossref | PubMed
  21. Foy BH, Carlson JCT, Reinertsen E, et al. Association of red blood cell distribution width with mortality risk in hospitalized adults with SARS-CoV-2 infection. JAMA Netw Open 2020;3:e2022058. 
    Crossref | PubMed
  22. García-Escobar A, Vera-Vera S, Tébar-Márquez D, et al. Neutrophil-to-lymphocyte ratio an inflammatory biomarker, and prognostic marker in heart failure, cardiovascular disease and chronic inflammatory diseases: new insights for a potential predictor of anti-cytokine therapy responsiveness. Microvasc Res 2023;150:104598. 
    Crossref | PubMed
  23. Jankowska EA, Rozentryt P, Witkowska A, et al. Iron deficiency: an ominous sign in patients with systolic chronic heart failure. Eur Heart J 2010;31:1872–80. 
    Crossref | PubMed
  24. Klip IT, Comin-Colet J, Voors AA, et al. Iron deficiency in chronic heart failure: an international pooled analysis. Am Heart J 2013;165:575–82.e3. 
    Crossref | PubMed
  25. Sangkhae V, Nemeth E. Regulation of the iron homeostatic hormone hepcidin. Adv Nutr 2017;8:126–36. 
    Crossref | PubMed
  26. Nemeth E, Tuttle MS, Powelson J, et al. Hepcidin regulates cellular iron efflux by binding to ferroportin and inducing its internalization. Science 2004;306:2090–3. 
    Crossref | PubMed
  27. Grote Beverborg N, Klip IT, Meijers WC, et al. Definition of iron deficiency based on the gold standard of bone marrow iron staining in heart failure patients. Circ Heart Fail 2018;11:e004519. 
    Crossref | PubMed
  28. Anker SD, Comin Colet J, Filippatos G, et al. Ferric carboxymaltose in patients with heart failure and iron deficiency. N Engl J Med 2009;361:2436–48. 
    Crossref | PubMed
  29. Ponikowski P, van Veldhuisen DJ, Comin-Colet J, et al. Beneficial effects of long-term intravenous iron therapy with ferric carboxymaltose in patients with symptomatic heart failure and iron deficiency†. Eur Heart J 2015;36:657–68. 
    Crossref | PubMed
  30. van Veldhuisen DJ, Ponikowski P, van der Meer P, et al. Effect of ferric carboxymaltose on exercise capacity in patients with chronic heart failure and iron deficiency. Circulation 2017;136:1374–83. 
    Crossref | PubMed
  31. Authors/Task Force Members:, McDonagh TA, Metra M, et al. 2023 Focused update of the 2021 ESC Guidelines for the diagnosis and treatment of acute and chronic heart failure: developed by the task force for the diagnosis and treatment of acute and chronic heart failure of the European Society of Cardiology (ESC) with the special contribution of the Heart Failure Association (HFA) of the ESC. Eur J Heart Fail 2024;26:5–17. 
    Crossref | PubMed
  32. Van Craenenbroeck EM, Conraads VM, Greenlaw N, et al. The effect of intravenous ferric carboxymaltose on red cell distribution width: a subanalysis of the FAIR-HF study. Eur J Heart Fail 2013;15:756–62. 
    Crossref | PubMed
  33. Emans ME, van der Putten K, van Rooijen KL, et al. Determinants of red cell distribution width (RDW) in cardiorenal patients: RDW is not related to erythropoietin resistance. J Card Fail 2011;17:626–33. 
    Crossref | PubMed
  34. Förhécz Z, Gombos T, Borgulya G, et al. Red cell distribution width in heart failure: prediction of clinical events and relationship with markers of ineffective erythropoiesis, inflammation, renal function, and nutritional state. Am Heart J 2009;158:659–66. 
    Crossref | PubMed
  35. van Zeben D, Bieger R, van Wermeskerken RK, et al. Evaluation of microcytosis using serum ferritin and red blood cell distribution width. Eur J Haematol 1990;44:106–9. 
    Crossref | PubMed
  36. Crespo-Leiro MG, Metra M, Lund LH, et al. Advanced heart failure: a position statement of the Heart Failure Association of the European Society of Cardiology. Eur J Heart Fail 2018;20:1505–35. 
    Crossref | PubMed
  37. Gao J, Chen J, Kramer M, et al. Interaction of the hereditary hemochromatosis protein HFE with transferrin receptor 2 is required for transferrin-induced hepcidin expression. Cell Metab 2009;9:217–27. 
    Crossref | PubMed
  38. Babitt JL, Huang FW, Wrighting DM, et al. Bone morphogenetic protein signaling by hemojuvelin regulates hepcidin expression. Nat Genet 2006;38:531–9. 
    Crossref | PubMed
  39. Lakhal S, Schödel J, Townsend ARM, et al. Regulation of type II transmembrane serine proteinase TMPRSS6 by hypoxia-inducible factors: new link between hypoxia signaling and iron homeostasis. J Biol Chem 2011;286:4090–7. 
    Crossref | PubMed
  40. Wang CY, Xu Y, Traeger L, et al. Erythroferrone lowers hepcidin by sequestering BMP2/6 heterodimer from binding to the BMP type I receptor ALK3. Blood 2020;135:453–6. 
    Crossref | PubMed
  41. Felker GM, Allen LA, Pocock SJ, et al. Red cell distribution width as a novel prognostic marker in heart failure: data from the CHARM Program and the Duke Databank. J Am Coll Cardiol 2007;50:40–7. 
    Crossref | PubMed
  42. Pascual-Figal DA, Bonaque JC, Redondo B, et al. Red blood cell distribution width predicts long-term outcome regardless of anaemia status in acute heart failure patients. Eur J Heart Fail 2009;11:840–6. 
    Crossref | PubMed
  43. Adams KF Jr, Mehra MR, Oren RM, et al. Prospective evaluation of the association between cardiac troponin T and markers of disturbed erythropoiesis in patients with heart failure. Am Heart J 2010;160:1142–8. 
    Crossref | PubMed
  44. van Kimmenade RRJ, Mohammed AA, Uthamalingam S, et al. Red blood cell distribution width and 1-year mortality in acute heart failure. Eur J Heart Fail 2010;12:129–36. 
    Crossref | PubMed
  45. Sotiropoulos K, Yerly P, Monney P, et al. Red cell distribution width and mortality in acute heart failure patients with preserved and reduced ejection fraction. ESC Heart Fail 2016;3:198–204. 
    Crossref | PubMed